Fig. 2: Genetic findings and polycystin (PC)1/2 two-dimensional domain structure.

(a) Pie charts indicating distribution of genetic findings in total autosomal dominant polycystic kidney disease (ADPKD) cohort, among PKD1 carriers, and among PKD2 carriers. LP likely pathogenic (diagnostic variant), P pathogenic (diagnostic variant). nF = number of families; nI = number of individuals. (b) Illustration of the two-dimensional domain structure of PC1 (red) and PC2 (blue), highlighting genetic findings of this study. Of note, known critical PC1 domains, such as REJ/GPS and C-type lectin, show clustering of pathogenic variants. ECL extracellular loop, ICL intracellular loop, LRR leucin-rich repeats, PH pore helix, WSC cell wall integrity and stress response component.